Induced degradation of glycosaminoglycans in Hurler's and Hunter's syndromes by plasma infusion.

نویسندگان

  • N Di Ferrante
  • B L Nichols
  • P V Donnelly
  • G Neri
  • R Hrgovcic
  • R K Berglund
چکیده

The effects of the administration of normal human plasma to patients affected by mucopolysaccharidoses I and II (Hurler's and Hunter's syndromes) have been evaluated. The infusion was followed by a decreased urinary excretion of relatively large molecular weight glycosaminoglycans and by an increased excretion of their products of degradation. Among the latter, products of the degradation of dermatan sulfate and heparan sulfate could be demonstrated. The results indicate that normal human plasma may contain those "factors" that are involved in the normal degradation of dermatan sulfate and heparan sulfate, that are missing in the diseased states.

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منابع مشابه

Hurler's, Hunter's and Morquio's syndromes. A biochemical study in the light of current views of the underlying defects.

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Some Paradoxial Observations Noted in the Prevalence of Hurlers and Hunter's Syndrome

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Decrease of urinary acid mucopolysaccharides in Hurler's syndrome after plasma infusion.

ORII, T., YAMAGUCHI, M., MINAMI, R. and NAKAO, T. Decrease of Urinary Acid Mueopolysaccharides in Hurler's Syndrome after Plasma Infusion. Tohoku J. exp. Med., 1974, 112 (4), 385-387 The fresh plasma infusion in patients affected by Hurler, Scheie or Morquio syndromes was followed by a decreased urinary excretion of chondroitin sulfate B or keratosulfate. Furthermore, in all of the patients the...

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Effect of leukocyte transfusion in a child with type II mucopolysaccharidosis.

Treatment of a child affected by type II mucopolysaccharidosis (Hunter's syndrome) with leukocyte transfusions produced dramatic biochemical and clinical changes. The biochemical changes, consisting of greatly increased urinary excretion of glycosaminoglycans and their products of degradation, were transient. The clinical changes, on the other hand, were protracted, which suggests that the mobi...

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عنوان ژورنال:
  • Proceedings of the National Academy of Sciences of the United States of America

دوره 68 2  شماره 

صفحات  -

تاریخ انتشار 1971